Unilateral benign yellow dot maculopathy.

Abstract Purpose To describe a unique case of unilateral benign yellow dot maculopathy. Observations A 25-year-man was evaluated after incidental finding of yellow dots in the right macula. Optical coherence tomography and electrophysiologic testing were unremarkable. The findings were in keeping with a diagnosis of benign yellow dot maculopathy. Conclusions and importance Benign yellow dot maculopathy is a recently described entity with either a sporadic or dominant inheritance pattern. This is the first known report of the characteristic findings of this phenotype presenting unilaterally.